Prenatal diagnosis of interruption of the aortic arch and its association with deletion of chromosome 22q11

Ultrasound Obstet Gynecol. 2002 Oct;20(4):327-31. doi: 10.1046/j.1469-0705.2002.00818.x.

Abstract

Objectives: Differentiation of interruption of the aortic arch (IAA) type A from type B by prenatal echocardiography is possible but difficult. We report nine consecutive cases of the prenatal detection of IAA and evaluate the feasibility of making a correct prenatal diagnosis with fetal echocardiography. The incidence of 22q11 microdeletion in our series, detected using fluorescent in situ hybridization (FISH) analysis, was determined.

Methods: Echocardiography and FISH for the DiGeorge critical region (22q11) were performed in all cases. The findings were confirmed by autopsy (three cases) or at postnatal surgery (six cases).

Results: On fetal echocardiography we identified six type B cases and three type A. FISH detected microdeletions in 22q11 in five of nine fetuses (four type B cases and an unusual association with type A in one case).

Conclusions: Our report confirms the feasibility of making a correct prenatal diagnosis of IAA and its different types, based on echocardiographic examination. Furthermore our data are consistent with previous reports indicating that type A and type B are distinct entities. In more than 50% of fetuses with IAA type B, 22q11 microdeletion and DiGeorge or velo-cardio-facial syndromes may be expected. IAA type A is not commonly associated with 22q11 hemizygosity.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aorta, Thoracic / abnormalities*
  • Chromosome Deletion*
  • Chromosomes, Human, Pair 22*
  • Feasibility Studies
  • Female
  • Fetal Diseases / diagnostic imaging*
  • Heart Septal Defects, Ventricular / diagnostic imaging
  • Humans
  • Pregnancy
  • Ultrasonography, Prenatal*