Chylotamponade: an unusual presentation of Gorham's syndrome

Ann Thorac Surg. 2003 May;75(5):1650-2. doi: 10.1016/s0003-4975(02)04776-8.

Abstract

Gorham's Syndrome, also known as massive osteolysis or "vanishing bone disease" results from lymphangiomatosis with adjacent bone resorption. Chylothorax is a common complication in cases of mediastinal involvement. We report a case of Gorham's Syndrome presenting as chylotamponade successfully treated with pericardial drainage, early parenteral nutritional support, bilateral pleurodesis for chylous effusions, and adjuvant external beam radiation.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Cardiac Tamponade / etiology*
  • Cardiac Tamponade / therapy
  • Female
  • Humans
  • Osteolysis, Essential / complications
  • Osteolysis, Essential / diagnosis*
  • Osteolysis, Essential / pathology
  • Osteolysis, Essential / therapy
  • Pericardial Effusion / etiology*
  • Pericardial Effusion / therapy
  • Ribs / pathology
  • Thoracic Vertebrae / pathology