The development of atypical haemolytic-uraemic syndrome is influenced by susceptibility factors in factor H and membrane cofactor protein: evidence from two independent cohorts

J Med Genet. 2005 Nov;42(11):852-6. doi: 10.1136/jmg.2005.030783. Epub 2005 Mar 22.

Abstract

Background: In both familial and sporadic atypical haemolytic-uraemic syndrome (aHUS), mutations have been reported in regulators of the alternative complement pathway including factor H (CFH), membrane cofactor protein (MCP), and the serine protease factor I (IF). A characteristic feature of both MCP and CFH associated HUS is reduced penetrance and variable inheritance; one possible explanation for this is that functional changes in complement proteins act as modifiers.

Objective: To examine single nucleotide polymorphisms in both CFH and MCP genes in two large cohorts of HUS patients (Newcastle and Paris).

Results: In both cohorts there was an association with HUS for both CFH and MCP alleles. CFH and MCP haplotypes were also significantly different in HUS patients compared with controls.

Conclusions: This study suggests that there are naturally occurring susceptibility factors in CFH and MCP for the development of atypical HUS.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alleles
  • Cohort Studies
  • Complement Factor H / genetics*
  • Complement Factor H / metabolism
  • Complement System Proteins
  • DNA Primers / chemistry
  • Gene Frequency
  • Genetic Predisposition to Disease*
  • Haplotypes
  • Hemolytic-Uremic Syndrome / diagnosis*
  • Hemolytic-Uremic Syndrome / genetics*
  • Humans
  • Membrane Cofactor Protein / genetics*
  • Membrane Cofactor Protein / metabolism
  • Mutation
  • Polymorphism, Single Nucleotide*
  • Receptors, Complement

Substances

  • DNA Primers
  • Membrane Cofactor Protein
  • Receptors, Complement
  • Complement Factor H
  • Complement System Proteins