[Periodic fever: the first Portuguese case-report of hyper-IgD syndrome (HIDS)]

Acta Med Port. 2004 Sep-Oct;17(5):391-4. Epub 2004 Dec 20.
[Article in Portuguese]

Abstract

Background: Periodic fever can have one of multiple causes. Among the hereditary periodic fever syndromes, hyper-IgD syndrome (HIDS) is a possible diagnosis, although, until now, no cases had been described in Portugal.

Case-report: We report a 25-year-old woman, with periodic fever since she was 8 months old. She had high serum IgD levels, and a molecular study of the mevalonate kinase gene was performed. A compound heterozygote was found for two mutations: V377I and T237S. This last mutation had not been observed before.

Discussion: We analyse the clinical features that made us think on HIDS as a possible diagnosis, and we highlight the features that are important for the differential diagnosis between HIDS and other periodic fevers.

Conclusions: HIDS is a possible diagnosis for patients with periodic fever, even in Portugal.

Publication types

  • Case Reports
  • English Abstract

MeSH terms

  • Adult
  • Familial Mediterranean Fever / complications*
  • Female
  • Humans
  • Hypergammaglobulinemia / etiology*
  • Immunoglobulin D*
  • Portugal
  • Syndrome

Substances

  • Immunoglobulin D