Bronchial atresia: the hidden pathology within a spectrum of prenatally diagnosed lung masses

J Pediatr Surg. 2006 Jan;41(1):61-5; discussion 61-5. doi: 10.1016/j.jpedsurg.2005.10.082.

Abstract

Purpose: This study was aimed at determining whether different congenital lung masses represent diverse manifestations of a single developmental abnormality associated with fetal airway obstruction.

Methods: We conducted a 3-year retrospective review of patients who underwent surgical resection of a prenatally diagnosed lung mass. Prenatal imaging was used to define mass position and its effect on adjacent organs. Lung specimens were examined through careful full-specimen microdissections, as well as by plain and contrast roentgenograms.

Results: Twenty-five patients underwent lung resection during this study period. Based on the final pathology reports, 56% were congenital cystic adenomatoid malformations, 12% were congenital lobar emphysemas, 8% were bronchopulmonary sequestrations, and 24% had features of both cystic adenomatoid malformation and bronchopulmonary sequestrations. No bronchogenic cysts were present in this series. Overall, bronchial atresia was identified in 77% of the examined specimens (n = 22) and was associated with all types of lung malformations.

Conclusions: Bronchial atresia is a common, unrecognized component of prenatally diagnosed congenital cystic adenomatoid malformations, bronchopulmonary sequestrations, congenital lobar emphysemas, and lesions of mixed pathology. Most congenital lung masses may be part of a spectrum of anomalies linked to obstruction of the developing fetal airway as an underlying component in their pathogenesis.

MeSH terms

  • Airway Obstruction / etiology
  • Fetal Diseases / etiology*
  • Fetal Diseases / pathology*
  • Humans
  • Infant, Newborn
  • Lung Diseases / complications*
  • Prenatal Diagnosis*
  • Pulmonary Atresia / diagnostic imaging
  • Pulmonary Atresia / etiology*
  • Pulmonary Atresia / pathology*
  • Radiography, Thoracic
  • Retrospective Studies