Clinical and biological features in the prognosis of adrenocortical cancer: poor outcome of cortisol-secreting tumors in a series of 202 consecutive patients

J Clin Endocrinol Metab. 2006 Jul;91(7):2650-5. doi: 10.1210/jc.2005-2730. Epub 2006 May 2.

Abstract

Context: Adrenocortical carcinomas (ACC) are rare tumors with a poor prognosis. Few reports concerning large and homogeneous series are available.

Objective: We aimed to determine the clinical characteristics and outcome of ACC and to identify prognostic factors.

Design and setting: This study is a descriptive and multivariate analysis of a cohort from a single endocrinology center.

Patients: A total of 202 consecutive patients with ACC were studied.

Results: The sex ratio (female to male) was 2.7. Mean age at diagnosis was 44 +/- 16 yr (range, 11-88 yr). We found that 154 patients (76%) had hypersecreting tumors [mostly cortisol and androgens (47%), cortisol alone (27%), or androgens alone (6%)] and 43 patients (21%) had metastases at diagnosis. At initial staging or during follow-up, 85 patients (42%) had liver metastases, 79 patients (39%) had lung metastases, and 20 patients had bone metastases (10%). The survival rate was 37% at 5 yr. Multivariate analysis identified the following independent prognostic factors associated with shorter survival: older age at diagnosis [hazard ratio (HR), 1.03; P < 0.0001], initial MacFarlane extension stages 3 (HR, 4.42; P = 0.005) and 4 (HR, 7.93; P < 0.0001), and cortisol hypersecretion (HR, 3.90; P < 0.0001). Treatment with 1,1-dichlorodiphenildichloroethane (o,p'DDD) in the 3 months after surgery increased the survival rate of patients with cortisol-secreting tumors (HR, 0.40; P = 0.04).

Conclusion: This study highlights the better prognosis of ACC diagnosed at a noninvasive local stage, the particularly poor prognosis of patients with cortisol-secreting tumors, and the beneficial effect of o,p'DDD therapy in this subgroup of patients.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adrenal Cortex Neoplasms / metabolism*
  • Adrenal Cortex Neoplasms / pathology
  • Adrenal Cortex Neoplasms / surgery
  • Adult
  • Analysis of Variance
  • Androgens / metabolism
  • Antineoplastic Agents, Hormonal / therapeutic use
  • Bone Neoplasms / secondary
  • Chemotherapy, Adjuvant
  • Female
  • Humans
  • Hydrocortisone / metabolism*
  • Liver Neoplasms / secondary
  • Lung Neoplasms / secondary
  • Male
  • Middle Aged
  • Mitotane / therapeutic use
  • Neoplasm Staging
  • Prognosis
  • Survival Rate

Substances

  • Androgens
  • Antineoplastic Agents, Hormonal
  • Mitotane
  • Hydrocortisone