Polydactyly with ectodermal defect, osteopenia, and mental delay

J Child Neurol. 2008 Jun;23(6):683-9. doi: 10.1177/0883073807309778. Epub 2008 Jan 8.

Abstract

Five members from 3 generations, including a 35-year-old woman and her 2 sons, both mentally impaired to a different degree, were studied in a tertiary care hospital. Anamnestic, clinical, neurological, and radiological evaluations were used to describe phenotypes. A and B postaxial polydactyly, transmitted likely as autosomal dominant, was associated with an extensive variability of phenotypic features: (1) cutaneous syndactyly, (2) nail-teeth dysplasia, (3) osteopenia, and (4) mental delay. The likelihood that the constellation of observations we report here is caused by mutation of a single gene that subsequently affects multiple physiological activities, although fascinating, remains to be proven. Instead, we hypothesize that it likely develops as a contiguous gene syndrome.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Bone Diseases, Metabolic / diagnosis
  • Bone Diseases, Metabolic / genetics*
  • Child
  • Chromosome Aberrations
  • Ectodermal Dysplasia / diagnosis
  • Ectodermal Dysplasia / genetics*
  • Female
  • Genes, Dominant / genetics
  • Genetic Diseases, Inborn / diagnosis
  • Genetic Diseases, Inborn / genetics
  • Humans
  • Intellectual Disability / diagnosis
  • Intellectual Disability / genetics*
  • Male
  • Nails, Malformed / diagnosis
  • Nails, Malformed / genetics
  • Pedigree
  • Phenotype
  • Polydactyly / diagnosis
  • Polydactyly / genetics*
  • Syndactyly / diagnosis
  • Syndactyly / genetics
  • Tooth Abnormalities / diagnosis
  • Tooth Abnormalities / genetics