Identification of a novel germ-line mutation in the TP53 gene in a Mexican family with Li-Fraumeni syndrome

World J Surg Oncol. 2009 Dec 17:7:97. doi: 10.1186/1477-7819-7-97.

Abstract

Background: Germ-line mutations of the TP53 gene are known to cause Li-Fraumeni syndrome, an autosomal, dominantly inherited, high-penetrance cancer-predisposition syndrome characterized by the occurrence of a variety of cancers, mainly soft tissue sarcomas, adrenocortical carcinoma, leukemia, breast cancer, and brain tumors.

Methods: Mutation analysis was based on Denaturing high performance liquid chromatography (DHPLC) screening of exons 2-11 of the TP53 gene, sequencing, and cloning of DNA obtained from peripheral blood lymphocytes.

Results: We report herein on Li Fraumeni syndrome in a family whose members are carriers of a novel TP53 gene mutation at exon 4. The mutation comprises an insertion/duplication of seven nucleotides affecting codon 110 and generating a new nucleotide sequence and a premature stop codon at position 150. With this mutation, the p53 protein that should be translated lacks the majority of the DNA binding domain.

Conclusion: To our knowledge, this specific alteration has not been reported previously, but we believe it is the cause of the Li-Fraumeni syndrome in this family.

MeSH terms

  • Adult
  • Aged
  • DNA Primers / chemistry
  • DNA Primers / genetics
  • Female
  • Germ-Line Mutation / genetics*
  • Humans
  • Li-Fraumeni Syndrome / genetics*
  • Male
  • Mexico
  • Middle Aged
  • Pedigree
  • Tumor Suppressor Protein p53 / genetics*
  • Young Adult

Substances

  • DNA Primers
  • TP53 protein, human
  • Tumor Suppressor Protein p53