A case of syndromic neutropenia and mutation in G6PC3

J Pediatr Hematol Oncol. 2011 Mar;33(2):138-40. doi: 10.1097/MPH.0b013e3181f46bf4.

Abstract

Background: A previously unrecognized syndrome with congenital neutropenia and various organ abnormalities has been described recently, caused by mutations in the gene encoding glucose-6-phosphatase, catalytic subunit 3 (G6PC3).

Observation: A 10-year-old boy from Ecuador suffering from severe neutropenia and multiple nonhematopoietic abnormalities was admitted to our department. We identified a novel mutation in the G6PC3 gene (c. 765_delAG; p.S255fs).

Conclusions: This is the first case of G6PC3 deficiency in a patient from South America, caused by a novel mutation in the G6PC3 gene. Our results give insights into the molecular and clinical variability of this disease.

Publication types

  • Case Reports

MeSH terms

  • Abnormalities, Multiple / genetics*
  • Abnormalities, Multiple / pathology
  • Cell Differentiation
  • Child
  • Congenital Bone Marrow Failure Syndromes
  • Glucose-6-Phosphatase / genetics*
  • Humans
  • Male
  • Mutation*
  • Neutropenia / complications
  • Neutropenia / congenital
  • Neutropenia / genetics
  • Neutropenia / pathology
  • Syndrome

Substances

  • Glucose-6-Phosphatase
  • G6PC3 protein, human

Supplementary concepts

  • Neutropenia, Severe Congenital, Autosomal Recessive 3