[Genetic screening of Gata4 and Nkx2.5 mutations in hereditary congenital heart defects: 5 familial cases]

Recenti Prog Med. 2011 Mar;102(3):120-5. doi: 10.1701/608.7068.
[Article in Italian]

Abstract

Single gene mutations in Gata4 and Nkx2.5 genes have been identified as a causative factor for various clinical forms of hereditary congenital heart diseases (CHDs), especially for cardiac septal defects. However, the role of Gata4 and Nkx2.5 mutations in familial CHD is not clear yet. We report 5 cases of familial CHD with a positive history of cardiac septal defects. Our data suggest that mutations of either the Gata4 or Nkx2.5 genes are very uncommonly found in familial cases of CHD, supporting the genetic heterogeneity of cardiac congenital defects and the limitation of genetic testing in clinical setting.

Publication types

  • Case Reports

MeSH terms

  • Child
  • Child, Preschool
  • Female
  • GATA4 Transcription Factor / genetics*
  • Genetic Testing*
  • Heart Defects, Congenital / genetics*
  • Homeobox Protein Nkx-2.5
  • Homeodomain Proteins / genetics*
  • Humans
  • Infant
  • Male
  • Middle Aged
  • Mutation*
  • Pedigree
  • Transcription Factors / genetics*

Substances

  • GATA4 Transcription Factor
  • GATA4 protein, human
  • Homeobox Protein Nkx-2.5
  • Homeodomain Proteins
  • NKX2-5 protein, human
  • Transcription Factors