[Clinical and molecular genetic analysis for a patient with glycogen storage disease Ⅰa]

Zhongguo Dang Dai Er Ke Za Zhi. 2012 Nov;14(11):856-8.
[Article in Chinese]

Abstract

Objective: To investigate the mutation of glucose-6-phosphatase gene (G6PC gene) in a patient with glycogen storage disease Ⅰa.

Methods: PCR was used to amplify all five exons of G6PC gene. The PCR products were directly sequenced to detect the mutations.

Results: A heterozygous 743G>A mutation was found in the patient and his mother, resulting in the substitution of glycine (G) by arginine (R) in codon 222(G222R) in the putative membrane-spanning domain in human G6Pase, but not in his father and his sister.

Conclusions: G222R mutation in G6PC gene was first identified in a patient with glycogen storage disease Ⅰa in mainland China.

Publication types

  • Case Reports
  • English Abstract

MeSH terms

  • Child, Preschool
  • Glucose-6-Phosphatase / genetics
  • Glycogen Storage Disease Type I / genetics*
  • Humans
  • Male
  • Mutation
  • Sequence Analysis, DNA

Substances

  • Glucose-6-Phosphatase