Molecular testing prognostic of low risk in epithelioid uveal melanoma in a child

Br J Ophthalmol. 2013 Mar;97(3):323-6. doi: 10.1136/bjophthalmol-2012-302561. Epub 2013 Jan 3.

Abstract

Aims: To characterise a histologically unusual paediatric uveal melanoma by gene expression and karyotypic profiling and assess prognosis.

Methods: The tumour was studied by histopathology, karyotype analysis, single nucleotide polymorphism and gene expression profile analysis for correlation with clinical outcome.

Results: The tumour had predominantly epithelioid histology. Karyotype analysis showed none of the poor prognosis features normally associated with uveal melanoma. single nucleotide polymorphism analysis revealed no imbalance at chromosome 3. Gene expression profiling indicated low risk disease.

Conclusions: We report a child remaining relapse-free 6 years after diagnosis of a very rare uveal melanoma, with poor prognosis epithelioid histology, but gene expression profiling that accurately predicted low risk disease.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Child, Preschool
  • Chromosomes, Human, Pair 3 / chemistry*
  • Female
  • Gene Expression Profiling / methods*
  • Gene Expression Regulation, Neoplastic*
  • Humans
  • Melanoma / diagnosis*
  • Melanoma / genetics
  • Melanoma / metabolism
  • Polymorphism, Single Nucleotide*
  • Prognosis
  • Reproducibility of Results
  • Uveal Neoplasms / diagnosis*
  • Uveal Neoplasms / genetics
  • Uveal Neoplasms / metabolism

Supplementary concepts

  • Uveal melanoma