Serial chitotriosidase measurements in sarcoidosis--two to five year follow-up study

Respir Med. 2014 May;108(5):775-82. doi: 10.1016/j.rmed.2014.02.002. Epub 2014 Feb 14.

Abstract

Introduction: Chitotriosidase (CTO) is a human chitinolytic enzyme secreted by activated macrophages and polymorphonuclear neutrophils. Albeit not specific for sarcoidosis, it is increased in over 90% of patients with active disease. The aims of this study were to correlate CTO measurements with clinical assessment of sarcoidosis and to test CTO as a marker of sarcoidosis relapse.

Methods: 95 patients were followed-up for 24-60 months. Serial CTO measurements were performed every 3-6 months and correlated to clinical symptoms, lung function (FVC and DLco) and chest X-ray. In 38 patients clinical outcome status (COS) at 5 years was determined.

Results: Initial CTO levels were significantly higher in patients with impaired FVC/DLco (p = 0.011 for both) but there was no correlation with standard chest X-ray stages. Patients with Loefgren's syndrome had significantly lower initial and control CTO level compared to other patients (p = 0.011 and p = 0.001, respectively). At follow-up there was a positive correlation of CTO and deterioration of clinical symptoms (p < 0.001), chest X-ray (p < 0.001) and FVC/DLco (p = 0.012 and p = 0.086, respectively). Control CTO levels were significantly lower in no disease groups versus minimal or persistent disease group as defined by COS (p = 0.003 and p < 0.001, respectively). At relapse CTO increased for 100% or more from baseline value in 12/14 patients.

Conclusions: It was shown that CTO correlates with certain sarcoidosis phenotypes (Loefgren's syndrome, COS) and that serial measurements of CTO correlate with clinical symptoms, chest radiographs and lung function.

Keywords: Chitotriosidase; Follow-up; Sarcoidosis.

MeSH terms

  • Adult
  • Aged
  • Antifungal Agents / therapeutic use
  • Biomarkers / blood
  • Blood Specimen Collection / methods
  • Clinical Enzyme Tests / methods
  • Drug Therapy, Combination
  • Female
  • Follow-Up Studies
  • Glucocorticoids / therapeutic use
  • Hexosaminidases / blood*
  • Humans
  • Male
  • Middle Aged
  • Prognosis
  • Prospective Studies
  • Pulmonary Diffusing Capacity / physiology
  • Radiography
  • Recurrence
  • Sarcoidosis / diagnosis*
  • Sarcoidosis / diagnostic imaging
  • Sarcoidosis / drug therapy
  • Sarcoidosis / physiopathology
  • Vital Capacity / physiology
  • Young Adult

Substances

  • Antifungal Agents
  • Biomarkers
  • Glucocorticoids
  • Hexosaminidases
  • chitotriosidase