Biophysical and structural characterization of a folded core domain within the proregion of growth and differentiation factor-5

FEBS J. 2014 Nov;281(21):4866-77. doi: 10.1111/febs.13025. Epub 2014 Sep 26.

Abstract

The structure and function(s) of the very large proregions of the transforming growth factor-β structure family are known in only a few cases. The proregion of growth and differentiation factor (GDF)5 comprises 354 residues. GDF5 therefore belongs to the group of those growth factors with the largest proregions. Here, we report a biophysical analysis of the proform (proGDF5) and the separate proregion. In the absence of the mature part, the proregion folds reversibly to form a monomeric polypeptide that is stabilized by an intramolecular disulfide bond. In the context of the mature part, i.e. in proGDF5, the proregion shows increased thermodynamic stability and contains a higher proportion of secondary structural elements than in its isolated form. A subdomain within the proregion represents a well-folded structure as monitored via biophysical analysis and NMR spectroscopy. Furthermore, two point mutations that are associated with skeletal malformations lead to reduced thermodynamic stability, which is interpreted on the basis of a homology model with the structure of the related latency-associated peptide, representing the proregion of transforming growth factor-β1.

Keywords: bone morphogenetic protein; domain coupling; proregion; subdomain; thermodynamics.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Amino Acid Substitution
  • Brachydactyly / genetics
  • Circular Dichroism
  • Cystine / analysis
  • Growth Differentiation Factor 5 / chemistry*
  • Growth Differentiation Factor 5 / drug effects
  • Growth Differentiation Factor 5 / physiology
  • Hot Temperature
  • Humans
  • Models, Molecular
  • Mutation, Missense
  • Nuclear Magnetic Resonance, Biomolecular
  • Point Mutation
  • Protein Conformation
  • Protein Denaturation
  • Protein Folding
  • Protein Precursors / chemistry
  • Protein Processing, Post-Translational
  • Protein Stability
  • Protein Structure, Secondary
  • Protein Structure, Tertiary
  • Recombinant Fusion Proteins / chemistry
  • Spectrometry, Fluorescence
  • Structure-Activity Relationship

Substances

  • GDF5 protein, human
  • Growth Differentiation Factor 5
  • Protein Precursors
  • Recombinant Fusion Proteins
  • Cystine