Hepatobiliary IgG4 Cholangiopathy: Case Series and Literature Review

Int J Surg Pathol. 2015 Oct;23(7):531-6. doi: 10.1177/1066896915596630. Epub 2015 Jul 27.

Abstract

IgG4 cholangiopathy is a recently described distinctive type of hepatobiliary manifestation of IgG4-related disease. This is often misdiagnosed as a malignancy of the hepatobiliary system on clinical presentation and imaging. Accurate diagnosis is crucial for appropriate management. Histopathology provides crucial information and is characterized by IgG4-positive lymphoplasmacytic infiltration with storiform fibrosis and obliterative phlebitis. We present the clinicopathological spectrum of a retrospective series of 6 cases of IgG4 cholangiopathy that clinically masqueraded as hepatobiliary malignancies.

Keywords: IgG4; cholangiopathy; hepatobiliary; obliterative phlebitis; storiform fibrosis.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Aged, 80 and over
  • Autoimmune Diseases / immunology
  • Autoimmune Diseases / pathology*
  • Bile Duct Diseases / immunology
  • Bile Duct Diseases / pathology*
  • Female
  • Fibrosis / immunology
  • Fibrosis / pathology
  • Humans
  • Immunoglobulin G*
  • Liver Diseases / immunology
  • Liver Diseases / pathology*
  • Male
  • Middle Aged
  • Plasma Cells / immunology
  • Plasma Cells / pathology*

Substances

  • Immunoglobulin G