Activation-Induced Cytidine Deaminase Expression in Human B Cell Precursors Is Essential for Central B Cell Tolerance

Immunity. 2015 Nov 17;43(5):884-95. doi: 10.1016/j.immuni.2015.10.002. Epub 2015 Nov 3.

Abstract

Activation-induced cytidine deaminase (AID), the enzyme-mediating class-switch recombination (CSR) and somatic hypermutation (SHM) of immunoglobulin genes, is essential for the removal of developing autoreactive B cells. How AID mediates central B cell tolerance remains unknown. We report that AID enzymes were produced in a discrete population of immature B cells that expressed recombination-activating gene 2 (RAG2), suggesting that they undergo secondary recombination to edit autoreactive antibodies. However, most AID+ immature B cells lacked anti-apoptotic MCL-1 and were deleted by apoptosis. AID inhibition using lentiviral-encoded short hairpin (sh)RNA in B cells developing in humanized mice resulted in a failure to remove autoreactive clones. Hence, B cell intrinsic AID expression mediates central B cell tolerance potentially through its RAG-coupled genotoxic activity in self-reactive immature B cells.

Keywords: AID-deficient patients; B cell development; B cell tolerance; activation-induced cytidine deaminase.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Animals
  • Apoptosis / genetics
  • Apoptosis / immunology
  • Case-Control Studies
  • Central Tolerance / genetics*
  • Central Tolerance / immunology*
  • Child
  • Child, Preschool
  • Cytidine Deaminase / genetics*
  • DNA-Binding Proteins / genetics
  • Female
  • Genes, Immunoglobulin / genetics
  • Genes, Immunoglobulin / immunology
  • Humans
  • Lymphocyte Activation / genetics
  • Lymphocyte Activation / immunology*
  • Male
  • Mice
  • Middle Aged
  • Nuclear Proteins / genetics
  • Precursor Cells, B-Lymphoid / immunology*
  • Recombination, Genetic / genetics
  • Recombination, Genetic / immunology
  • Somatic Hypermutation, Immunoglobulin / genetics
  • Somatic Hypermutation, Immunoglobulin / immunology
  • Young Adult

Substances

  • DNA-Binding Proteins
  • Nuclear Proteins
  • RAG2 protein, human
  • Cytidine Deaminase