Health-related quality of life among children with Turner syndrome: controlled cross-sectional study

J Pediatr Endocrinol Metab. 2017 Aug 28;30(8):863-868. doi: 10.1515/jpem-2017-0026.

Abstract

Background: The aim of the study was to assess health-related quality of life (HR-QoL) in children with Turner syndrome in comparison with controls.

Methods: We prospectively recruited 16 female girls with Turner syndrome (mean age 15.2±2.6 years) and 78 female controls (mean age 12.7±2.8 years) in randomly selected schools. We used the PedsQL, a generic HR-QoL questionnaire (self and parents' versions).

Results: Global HR-QoL scores in Turner syndrome were lower than controls for self-reports (respectively, 74.3±3.0 vs. 82.8±1.3, p=0.01) and parents' reports (62.7±3.8 vs. 80.1±1.7, p<0.0001). In Turner syndrome, self-reported HR-QoL was impaired in school functioning (70.6±4.0 vs. 80.71±1.7, p=0.02), social functioning (78.2±4.0 vs. 90.4±1.8, p<0.01) and physical functioning (78.5±3.2 vs. 87.1±1.4, p=0.02), but not in emotional functioning. Parents' reported HR-QoL was impaired in all four dimensions.

Conclusions: HR-QoL was impaired in this cohort of young females with Turner syndrome, as in previously reported adult studies. In addition to medical treatment and routine clinical follow-up, female girls and teenagers with Turner syndrome should also be supported psychologically by social, educational and psychotherapeutic interventions that aim to address their self-esteem and emotional difficulties.

Keywords: PedsQL; Turner syndrome; health-related quality of life; pediatrics.

MeSH terms

  • Adolescent
  • Child
  • Cross-Sectional Studies
  • Female
  • Health Status*
  • Humans
  • Parents / psychology
  • Quality of Life / psychology*
  • Self Concept*
  • Self Report
  • Social Adjustment*
  • Surveys and Questionnaires
  • Turner Syndrome / psychology*