Is Behçet's disease a 'class 1-opathy'? The role of HLA-B*51 in the pathogenesis of Behçet's disease

Clin Exp Immunol. 2018 Jan;191(1):11-18. doi: 10.1111/cei.13049. Epub 2017 Oct 6.

Abstract

The association between carriage of the human leucocyte antigen (HLA)-B*51 allele and development of Behçet's disease (BD) has been known since the early 1970s, but the exact mechanisms responsible for its role in pathogenesis remain much-debated. In an effort to explain the disease process, it has been suggested that BD constitutes one of a newly termed group of diseases, the 'MHC-I-opathies'. Other MHC-I-opathies include ankylosing spondylitis and HLA-B*27-associated spondyloarthropathies and HLA-C*0602-associated skin psoriasis. Recent work analysing the peptidome of HLA-B*51 suggests that altered peptide presentation by HLA-B*51 is vital to the disease process. In this review, we argue that immune receptor interactions with HLA-B*51 or the HLA-B*51-peptide complex could lead to development of inflammation in BD. The evidence for CD8+ T cell involvement is weak, and based on emerging studies it seems more likely that natural killer (NK) or other cell interactions, perhaps mediated by leucocyte immunoglobulin-like receptor (LILR) or killer immunoglobulin-like receptor (KIR) receptors, are culpable in pathogenesis. HLA misfolding leading directly to inflammation is another hypothesis for BD pathogenesis that deserves greater investigation. Ultimately, greater understanding of HLA-B*51's unique role in BD will probably lead to improved development of therapeutic strategies.

Keywords: antigen presentation/processing; autoimmunity; autoinflammatory disease.

Publication types

  • Review
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alleles
  • Antigen Presentation / immunology
  • Autoimmunity / genetics
  • Autoimmunity / immunology
  • Behcet Syndrome / etiology*
  • Behcet Syndrome / metabolism
  • Cytokines / metabolism
  • Disease Susceptibility
  • Epitopes / chemistry
  • Epitopes / immunology
  • Genetic Predisposition to Disease
  • HLA-B51 Antigen / chemistry
  • HLA-B51 Antigen / genetics*
  • HLA-B51 Antigen / immunology*
  • HLA-B51 Antigen / metabolism
  • Humans
  • Killer Cells, Natural / immunology
  • Killer Cells, Natural / metabolism
  • Microbiota
  • Peptides / chemistry
  • Peptides / immunology
  • Protein Folding
  • T-Lymphocyte Subsets / immunology
  • T-Lymphocyte Subsets / metabolism
  • Th17 Cells / immunology
  • Th17 Cells / metabolism

Substances

  • Cytokines
  • Epitopes
  • HLA-B51 Antigen
  • Peptides