Towards the Identification of Molecular Biomarkers of Spinocerebellar Ataxia Type 3 (SCA3)/Machado-Joseph Disease (MJD)

Adv Exp Med Biol. 2018:1049:309-319. doi: 10.1007/978-3-319-71779-1_16.

Abstract

Whereas spinocerebellar ataxia type 3 (SCA3)/Machado-Joseph disease (MJD) remains an untreatable disorder, disease-modifying compounds have begun being tested in the context of clinical trials; their success is dependent on the sensitivity of the methods used to measure subtle therapeutic benefits. Thus, efforts are being made to propose a battery of potential outcome measures, including molecular biomarkers (MBs), which remain to be identified; MBs are particularly pertinent if SCA3 trials are expected to enroll preataxic subjects. Recently, promising candidate MBs of SCA3 have emerged from gene expression studies. In this chapter we provide a synthesis of the cross-sectional and pilot longitudinal studies of blood-based transcriptional biomarkers conducted so far. Other alterations with potential to track the progression of SCA3, such as those involving mitochondrial DNA (mtDNA) are also referred. It is expected that a set of molecular biomarkers can be identified; these will be used in complementarity with clinical and imaging markers to fully track SCA3, from its preataxic phase to the disease stage.

Keywords: Biochemical markers; Polyglutamine disorders; RNA; State biomarkers; Trait biomarkers; Transcriptional dysregulation.

Publication types

  • Review

MeSH terms

  • Biomarkers / metabolism
  • DNA, Mitochondrial* / genetics
  • DNA, Mitochondrial* / metabolism
  • Gene Expression Profiling*
  • Gene Expression Regulation*
  • Humans
  • Machado-Joseph Disease* / diagnosis
  • Machado-Joseph Disease* / genetics
  • Machado-Joseph Disease* / metabolism

Substances

  • Biomarkers
  • DNA, Mitochondrial