Recruitment of DNA Repair MRN Complex by Intrinsically Disordered Protein Domain Fused to Cas9 Improves Efficiency of CRISPR-Mediated Genome Editing

Biomolecules. 2019 Oct 8;9(10):584. doi: 10.3390/biom9100584.

Abstract

CRISPR/Cas9 is a powerful tool for genome editing in cells and organisms. Nevertheless, introducing directed templated changes by homology-directed repair (HDR) requires the cellular DNA repair machinery, such as the MRN complex (Mre11/Rad50/Nbs1). To improve the process, we tailored chimeric constructs of Cas9, in which SpCas9 was fused at its N- or C-terminus to a 126aa intrinsically disordered domain from HSV-1 alkaline nuclease (UL12) that recruits the MRN complex. The chimeric Cas9 constructs were two times more efficient in homology-directed editing of endogenous loci in tissue culture cells. This effect was dependent upon the MRN-recruiting activity of the domain and required lower amounts of the chimeric Cas9 in comparison with unmodified Cas9. The new constructs improved the yield of edited cells when making endogenous point mutations or inserting small tags encoded by oligonucleotide donor DNA (ssODN), and also with larger insertions encoded by plasmid DNA donor templates. Improved editing was achieved with both transfected plasmid-encoded Cas9 constructs as well as recombinant Cas9 protein transfected as ribonucleoprotein complexes. Our strategy was highly efficient in restoring a genetic defect in a cell line, exemplifying the possible implementation of our strategy in gene therapy. These constructs provide a simple approach to improve directed editing.

Keywords: CRISPR/Cas9; Gene targeting; endogenous mutagenesis in cell lines; genome editing; homology-directed repair.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Acid Anhydride Hydrolases / metabolism
  • CRISPR-Associated Protein 9 / metabolism*
  • CRISPR-Cas Systems
  • Cell Cycle Proteins / metabolism
  • DNA Repair
  • DNA Repair Enzymes / metabolism*
  • DNA-Binding Proteins / metabolism
  • Deoxyribonucleases / chemistry*
  • Deoxyribonucleases / genetics
  • Deoxyribonucleases / metabolism
  • Gene Editing / methods*
  • Genetic Engineering
  • HCT116 Cells
  • HEK293 Cells
  • HeLa Cells
  • Herpesvirus 1, Human / genetics
  • Herpesvirus 1, Human / metabolism*
  • Humans
  • MRE11 Homologue Protein / metabolism
  • Nuclear Proteins / metabolism
  • Protein Domains
  • Recombinant Fusion Proteins / metabolism
  • Viral Proteins / chemistry*
  • Viral Proteins / genetics
  • Viral Proteins / metabolism

Substances

  • Cell Cycle Proteins
  • DNA-Binding Proteins
  • MRE11 protein, human
  • NBN protein, human
  • Nuclear Proteins
  • Recombinant Fusion Proteins
  • Viral Proteins
  • CRISPR-Associated Protein 9
  • Deoxyribonucleases
  • MRE11 Homologue Protein
  • UL12 protein, herpes simplex virus 1
  • Acid Anhydride Hydrolases
  • RAD50 protein, human
  • DNA Repair Enzymes