Clinicopathological characteristics and outcome of patients with fibrillary glomerulonephritis: DNAJB9 is a valuable histologic marker

J Nephrol. 2021 Jun;34(3):883-892. doi: 10.1007/s40620-020-00783-4. Epub 2020 Jun 18.

Abstract

Background: Fibrillary glomerulonephritis (FGN) is a rare glomerular disease. DNAJB9 as a new reliable diagnostic marker for the diagnosis of FGN was discovered recently. To investigate the clinicopathological features and prognosis of DNAJB9-positive FGN, we report on a case series in a single center in China.

Methods: DNAJB9 immunohistochemistry was performed on renal biopsy samples from patients with FGN (n = 7), and non-FGN glomerular diseases (n = 27) were used as controls. The patients with DNAJB9-positive FGN were retrospectively analyzed.

Results: Strong DNAJB9 staining of glomerular extracellular deposits was observed in 6 cases of originally diagnosed FGN. One man and 5 women with a median age of 26 years were studied. The patients presented with renal insufficiency in 1 case, proteinuria in 6 cases, nephrotic syndrome in 3 cases, and microscopic hematuria in 2 cases. The histologic pattern was mesangial proliferative glomerulonephritis in 1 case and membranoproliferative glomerulonephritis in 5 cases. The glomerular deposits stained for polytypic IgG and both kappa and lambda in 3 cases, polytypic IgG without kappa or lambda in 1, monotypic IgG1-kappa in 1 and IgG1-lambda in 1. Extraglomerular deposits were identified in all cases. Congo red positivity was observed in 3 cases. All of the patients received renin-angiotensin-aldosterone system blockade and 5 of them received glucocorticoid and/or immunosuppression. At a median time of 36.2 months after biopsy, 2 cases had partial remission, 3 cases displayed no remission, and 1 case progressed to end-stage renal disease.

Conclusions: Extraglomerular deposits in the FGN were common. Monotypic FGN was found in young patients with a favorable renal outcome.

Keywords: DNAJB9; Fibrillary glomerulonephritis; Immunohistochemistry; Membranoproliferative glomerulonephritis.

MeSH terms

  • Adult
  • Female
  • Glomerulonephritis* / metabolism
  • HSP40 Heat-Shock Proteins* / metabolism
  • Humans
  • Male
  • Membrane Proteins*
  • Molecular Chaperones*
  • Retrospective Studies

Substances

  • DNAJB9 protein, human
  • HSP40 Heat-Shock Proteins
  • Membrane Proteins
  • Molecular Chaperones