Tracing the mutated HTT and haplotype of the African ancestor who spread Huntington disease into the Middle East

Genet Med. 2020 Nov;22(11):1903-1908. doi: 10.1038/s41436-020-0895-1. Epub 2020 Jul 14.

Abstract

Purpose: We aimed to determine the origin and genetic characteristics of Huntington disease (HD) in the Middle East.

Methods: We performed genetic and genealogical analyses to establish the ancestral origin of the HTT pathgenic variant from a large kindred from Oman (hereafter called the OM-HD-01 pedigree) by single-nucleotide polymorphism and dense haplotype analysis genotyping.

Results: We traced the oldest ancestry of the largest, eight-generation, OM-HD-01 pedigree (n = 302 subjects, with 54 showing manifest HD) back to sub-Saharan Africa and identified a unique HD haplotype carried by all pedigree members, which consisted of portions of the C6 and C9 haplotypes and was carried by all affected members. Such a unique HD haplotype was of African origin and appeared to be associated with large CAG repeat expansions on average and high frequency of juvenile-onset HD. Three other families from the same area were also identified and found carrying a Caucasian HD haplotype A, also shared by most families of Arab ancestry.

Conclusion: Mutated HTT spread into Middle East with a unique haplotype of African origin, appeared to be associated with juvenile-onset, a HD condition frequently occurring in Black Africans, and may have a significant impact on further development of novel targeted genetic therapies.

Keywords: HTT; Huntington disease; SNP; haplotype analysis; juvenile-onset Huntington disease.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alleles
  • Haplotypes
  • Humans
  • Huntingtin Protein / genetics
  • Huntington Disease* / epidemiology
  • Huntington Disease* / genetics
  • Middle East / epidemiology
  • White People

Substances

  • HTT protein, human
  • Huntingtin Protein