FEN1 endonuclease as a therapeutic target for human cancers with defects in homologous recombination

Proc Natl Acad Sci U S A. 2020 Aug 11;117(32):19415-19424. doi: 10.1073/pnas.2009237117. Epub 2020 Jul 27.

Abstract

Synthetic lethality strategies for cancer therapy exploit cancer-specific genetic defects to identify targets that are uniquely essential to the survival of tumor cells. Here we show RAD27/FEN1, which encodes flap endonuclease 1 (FEN1), a structure-specific nuclease with roles in DNA replication and repair, and has the greatest number of synthetic lethal interactions with Saccharomyces cerevisiae genome instability genes, is a druggable target for an inhibitor-based approach to kill cancers with defects in homologous recombination (HR). The vulnerability of cancers with HR defects to FEN1 loss was validated by studies showing that small-molecule FEN1 inhibitors and FEN1 small interfering RNAs (siRNAs) selectively killed BRCA1- and BRCA2-defective human cell lines. Furthermore, the differential sensitivity to FEN1 inhibition was recapitulated in mice, where a small-molecule FEN1 inhibitor reduced the growth of tumors established from drug-sensitive but not drug-resistant cancer cell lines. FEN1 inhibition induced a DNA damage response in both sensitive and resistant cell lines; however, sensitive cell lines were unable to recover and replicate DNA even when the inhibitor was removed. Although FEN1 inhibition activated caspase to higher levels in sensitive cells, this apoptotic response occurred in p53-defective cells and cell killing was not blocked by a pan-caspase inhibitor. These results suggest that FEN1 inhibitors have the potential for therapeutically targeting HR-defective cancers such as those resulting from BRCA1 and BRCA2 mutations, and other genetic defects.

Keywords: DNA repair; DNA replication; cancer therapy; homologous recombination; synthetic lethality.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Antineoplastic Agents / pharmacology*
  • BRCA1 Protein / deficiency
  • BRCA1 Protein / genetics
  • BRCA2 Protein / deficiency
  • BRCA2 Protein / genetics
  • Cell Line, Tumor
  • DNA Damage / drug effects
  • DNA Repair / drug effects
  • DNA Replication / drug effects
  • Flap Endonucleases / antagonists & inhibitors*
  • Flap Endonucleases / genetics
  • Genomic Instability / genetics
  • Homologous Recombination / drug effects*
  • Humans
  • Mice
  • Neoplasms / drug therapy
  • Neoplasms / genetics*
  • RNA, Small Interfering / pharmacology
  • Saccharomyces cerevisiae
  • Saccharomyces cerevisiae Proteins / genetics
  • Small Molecule Libraries / pharmacology
  • Synthetic Lethal Mutations
  • Xenograft Model Antitumor Assays

Substances

  • Antineoplastic Agents
  • BRCA1 Protein
  • BRCA1 protein, human
  • BRCA2 Protein
  • BRCA2 protein, human
  • RNA, Small Interfering
  • Saccharomyces cerevisiae Proteins
  • Small Molecule Libraries
  • Flap Endonucleases
  • FEN1 protein, human
  • RAD27 protein, S cerevisiae