Neutral ceramidase deficiency protects against cisplatin-induced acute kidney injury

J Lipid Res. 2022 Mar;63(3):100179. doi: 10.1016/j.jlr.2022.100179. Epub 2022 Feb 10.

Abstract

Cisplatin is a commonly used chemotherapeutic for the treatment of many solid organ cancers; however, its effectiveness is limited by the development of acute kidney injury (AKI) in 30% of patients. AKI is driven by proximal tubule cell death, leading to rapid decline in renal function. It has previously been shown that sphingolipid metabolism plays a role in regulating many of the biological processes involved in cisplatin-induced AKI. For example, neutral ceramidase (nCDase) is an enzyme responsible for converting ceramide into sphingosine, which is then phosphorylated to become sphingosine-1-phosphate, and our lab previously demonstrated that nCDase knockout (nCDase-/-) in mouse embryonic fibroblasts led to resistance to nutrient and energy deprivation-induced cell death via upregulation of autophagic flux. In this study, we further characterized the role of nCDase in AKI by demonstrating that nCDase-/- mice are resistant to cisplatin-induced AKI. nCDase-/- mice display improved kidney function, reduced injury and structural damage, lower rates of apoptosis, and less ER stress compared to wild-type mice following cisplatin treatment. Although the mechanism of protection is still unknown, we propose that it could be mediated by increased autophagy, as chloroquine treatment resensitized nCDase-/- mice to AKI development. Taken together, we conclude that nCDase may represent a novel target to prevent cisplatin-induced nephrotoxicity.

Keywords: ER stress; animal models; autophagy; ceramide; chemotherapy; chloroquine; cisplatin; renal disease; sphingosine metabolism; sphingosine-1-phosphate.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, U.S. Gov't, Non-P.H.S.

MeSH terms

  • Acute Kidney Injury* / chemically induced
  • Acute Kidney Injury* / prevention & control
  • Animals
  • Apoptosis / physiology
  • Cisplatin / adverse effects
  • Farber Lipogranulomatosis*
  • Fibroblasts / metabolism
  • Humans
  • Mice
  • Neutral Ceramidase / metabolism

Substances

  • Neutral Ceramidase
  • Cisplatin