CRISPR/Cas9-mediated abrogation of CD95L/CD95 signaling-induced glioma cell growth and immunosuppression increases survival in murine glioma models

J Neurooncol. 2022 Nov;160(2):299-310. doi: 10.1007/s11060-022-04137-x. Epub 2022 Nov 10.

Abstract

Purpose: Glioblastoma is the most common brain tumor in adults and is virtually incurable. Therefore, new therapeutic strategies are urgently needed. Over the last decade, multiple growth-promoting functions have been attributed to CD95, a prototypic death receptor well characterized as an apoptosis mediator upon CD95L engagement. Strategic targeting of non-apoptotic or apoptotic CD95 signaling may hold anti-glioblastoma potential. Due to its antithetic nature, understanding the constitutive role of CD95 signaling in glioblastoma is indispensable.

Methods: We abrogated constitutive Cd95 and Cd95l gene expression by CRISPR/Cas9 in murine glioma models and characterized the consequences of gene deletion in vitro and in vivo.

Results: Expression of canonical CD95 but not CD95L was identified in mouse glioma cells in vitro. Instead, a soluble isoform-encoding non-canonical Cd95l transcript variant was detected. In vivo, an upregulation of the membrane-bound canonical CD95L form was revealed. Cd95 or Cd95l gene deletion decreased cell growth in vitro. The growth-supporting role of constitutive CD95 signaling was validated by Cd95 re-transfection, which rescued growth. In vivo, Cd95 or Cd95l gene deletion prolonged survival involving tumor-intrinsic and immunological mechanisms in the SMA-497 model. In the GL-261 model, that expresses no CD95, only CD95L gene deletion prolonged survival, involving a tumor-intrinsic mechanism.

Conclusion: Non-canonical CD95L/CD95 interactions are growth-promoting in murine glioma models, and glioma growth and immunosuppression may be simultaneously counteracted by Cd95l gene silencing.

Keywords: CD95; CD95L; CRISPR/Cas9; Glioblastoma; Immunosuppression.

MeSH terms

  • Animals
  • Apoptosis / physiology
  • Brain Neoplasms* / metabolism
  • Brain Neoplasms* / pathology
  • CRISPR-Cas Systems
  • Fas Ligand Protein / genetics
  • Fas Ligand Protein / metabolism
  • Glioblastoma* / metabolism
  • Glioblastoma* / pathology
  • Glioma* / metabolism
  • Glioma* / pathology
  • Immunosuppression Therapy
  • Mice
  • fas Receptor / genetics
  • fas Receptor / metabolism

Substances

  • Fas Ligand Protein
  • fas Receptor