Randomized controlled trial of linaclotide in children aged 6-17 years with functional constipation

J Pediatr Gastroenterol Nutr. 2024 May;78(5):1059-1068. doi: 10.1002/jpn3.12184. Epub 2024 Mar 27.

Abstract

Objectives: Linaclotide, a guanylate cyclase-C agonist, was recently approved in the United States for treatment of children 6-17 years old with functional constipation (FC). This study evaluated the safety and efficacy of several linaclotide doses in children 6-17 years old with FC.

Methods: In this multicenter, randomized, double-blind, placebo-controlled phase 2 study, 173 children with FC (based on Rome III criteria) were randomized to once-daily linaclotide (A: 9 or 18 μg, B: 18 or 36 μg, or C: 36 or 72 μg) or placebo in a 1:1:1:1 ratio for 6- to 11-year-olds (dosage determined by weight: 18 to <35 or ≥35 kg) and linaclotide (18, 36, 72, or 145 μg) or placebo in a 1:1:1:1:1 ratio for 12- to 17-year-olds. The primary efficacy endpoint was change from baseline in weekly spontaneous bowel movement (SBM) frequency throughout the 4-week treatment period. Adverse events (AE), clinical laboratory values, and electrocardiograms were monitored.

Results: Efficacy and safety were assessed in 173 patients (52.0% aged 6-11 years; 48.0% aged 12-17 years); 162 (93.6%) completed the treatment period. A numerical improvement in mean SBM frequency was observed with increasing linaclotide doses (1.90 in 6- to 11-year-olds [36 or 72 μg] and 2.86 in 12- to 17-year-olds [72 μg]). The most reported treatment-emergent AE was diarrhea, with most cases being mild; none were severe.

Conclusions: Linaclotide was well tolerated in this pediatric population, with a trend toward efficacy in the higher doses, warranting further evaluation.

Keywords: constipation; functional GI diseases; pediatric gastroenterology; small intestine.

Publication types

  • Randomized Controlled Trial
  • Multicenter Study
  • Clinical Trial, Phase II
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Child
  • Constipation* / drug therapy
  • Defecation / drug effects
  • Dose-Response Relationship, Drug
  • Double-Blind Method
  • Female
  • Gastrointestinal Agents / administration & dosage
  • Gastrointestinal Agents / therapeutic use
  • Guanylyl Cyclase C Agonists* / administration & dosage
  • Guanylyl Cyclase C Agonists* / therapeutic use
  • Humans
  • Male
  • Peptides* / administration & dosage
  • Peptides* / adverse effects
  • Peptides* / therapeutic use
  • Treatment Outcome

Substances

  • linaclotide
  • Peptides
  • Guanylyl Cyclase C Agonists
  • Gastrointestinal Agents