Clinical and genetic characteristics of BAP1-mutated non-uveal and uveal melanoma

Front Immunol. 2024 Jun 5:15:1383125. doi: 10.3389/fimmu.2024.1383125. eCollection 2024.

Abstract

Background: Screening for gene mutations has become routine clinical practice across numerous tumor entities, including melanoma. BAP1 gene mutations have been identified in various tumor types and acknowledged as a critical event in metastatic uveal melanoma, but their role in non-uveal melanoma remains inadequately characterized.

Methods: A retrospective analysis of all melanomas sequenced in our department from 2014-2022 (n=2650) was conducted to identify BAP1 mutated samples. Assessment of clinical and genetic characteristics was performed as well as correlations with treatment outcome.

Results: BAP1 mutations were identified in 129 cases and distributed across the entire gene without any apparent hot spots. Inactivating BAP1 mutations were more prevalent in uveal (55%) compared to non-uveal (17%) melanomas. Non-uveal BAP1 mutated melanomas frequently exhibited UV-signature mutations and had a significantly higher mutation load than uveal melanomas. GNAQ and GNA11 mutations were common in uveal melanomas, while MAP-Kinase mutations were frequent in non-uveal melanomas with NF1, BRAF V600 and NRAS Q61 mutations occurring in decreasing frequency, consistent with a strong UV association. Survival outcomes did not differ among non-uveal melanoma patients based on whether they received targeted or immune checkpoint therapy, or if their tumors harbored inactivating BAP1 mutations.

Conclusion: In contrast to uveal melanomas, where BAP1 mutations serve as a significant prognostic indicator of an unfavorable outcome, BAP1 mutations in non-uveal melanomas are primarily considered passenger mutations and do not appear to be relevant from a prognostic or therapeutic perspective.

Keywords: BAP1; immunotherapy; mutation profiling; non-uveal melanoma; uveal melanoma.

MeSH terms

  • Adult
  • Aged
  • Aged, 80 and over
  • Female
  • Humans
  • Male
  • Melanoma* / genetics
  • Melanoma* / mortality
  • Melanoma* / therapy
  • Middle Aged
  • Mutation*
  • Prognosis
  • Retrospective Studies
  • Tumor Suppressor Proteins* / genetics
  • Ubiquitin Thiolesterase* / genetics
  • Uveal Neoplasms* / genetics
  • Uveal Neoplasms* / mortality
  • Uveal Neoplasms* / therapy

Substances

  • Ubiquitin Thiolesterase
  • BAP1 protein, human
  • Tumor Suppressor Proteins

Supplementary concepts

  • Uveal melanoma

Grants and funding

The author(s) declare financial support was received for the research, authorship, and/or publication of this article. This work was in part supported by Bristol Myers Squibb for the multicenter translational study “Tissue Registry in Melanoma” (TRIM) within the framework of the skin cancer registry ADOREG of the German Dermatologic Cooperative Oncology Group (DeCOG). J-MP was supported by the DFG (German Research Foundation)funded Clinician Scientist Program of the University Medicine Essen Clinician Scientist Academy (UMEA) (FU 356/12-1).