Recurrent Hypoglycemia in a Non-diabetic Female: A Case Study on Doege-Potter Syndrome

Cureus. 2024 Jun 27;16(6):e63329. doi: 10.7759/cureus.63329. eCollection 2024 Jun.

Abstract

Solitary fibrous tumors (SFT) are mesenchymal cell tumors that may arise from any site throughout the body. A small percentage of patients with SFT develop non-islet cell tumor-induced hypoglycemia (NICTH), eponymously termed Doege-Potter Syndrome (DPS). DPS is characterized by severe, refractory hypoinsulinemic hypoglycemia. Diagnosis of SFT is dependent on histologic findings and immunohistochemistry (IHC). NAB2-STAT6 gene fusions are pathognomonic for SFT but may be difficult to identify in routine cytogenetic studies. STAT6 IHC is a highly sensitive and specific surrogate for the NAB2-STAT6 gene fusion. Total resection of the tumor remains the gold-standard definitive treatment of SFT of the pleura. Palliative tumor debulking is recommended if total resection is not feasible. We here report a case of DPS in a 73-year-old female, managed with palliative care.

Keywords: endocrinology; hypoglycemia; recurrent hypoglycemia; solitary fibrous pleural tumour; solitary fibrous tumor.

Publication types

  • Case Reports