Apolipoprotein E5 (Glu212-->Lys): increased binding to cell surface proteoglycans but decreased uptake and lysosomal degradation in cultured fibroblasts

J Lipid Res. 1996 Aug;37(8):1632-45.

Abstract

A new apolipoprotein (apo) E variant, apoE5 (Glu212-->Lys) was identified in a Turkish family. The variant was due to a point mutation (CAG-->AAG) at the first nucleotide position of the codon encoding amino acid residue 212 of the mature apoE. The 23-year-old index patient was heterozygous for the mutation. Examination of the proband's kindred revealed six heterozygous and two homozygous mutation carriers. Compared to non-carriers, carriers of the mutation had slightly higher triglycerides (1.25 versus 1.11 g/l) and lower HDL cholesterol (0.36 versus 0.41 g/l). Very low density lipoproteins (VLDL) from an apoE5 (Glu212-->Lys) homozygote displayed enhanced binding (+17%, P < 0.05), but decreased uptake (-35%, P < 0.0001) and degradation (-51%, P < 0.0001) in cultured fibroblasts, compared to E3/3-VLDL. The region of the apoE molecule surrounding residue 212 contains a heparin binding domain. Consistently, the enhanced cell surface binding of E5/5-VLDL was observed in "wild-type" Chinese hamster ovary cells (+19%, P < 0.05), but not in proteoglycan-deficient cells. The binding of E5/5-VLDL to heparin was increased (+22%, P < 0.05). As the endocytosis of apoE-containing particles involves the transfer of proteoglycan-bound ligands to lipoprotein receptors, the stronger binding of apoE5 (Glu212-->Lys) to proteoglycans could reduce the rate at which the mutant is finally delivered to endocytotic pathways. These data may provide evidence for a functionally important heparin binding site around amino acid residue 212 of the apoE molecule in vivo.

Publication types

  • Comparative Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Animals
  • Apolipoproteins E / chemistry
  • Apolipoproteins E / genetics
  • Apolipoproteins E / metabolism*
  • Binding, Competitive
  • CHO Cells / cytology
  • CHO Cells / metabolism
  • Cells, Cultured
  • Child
  • Child, Preschool
  • Cricetinae
  • Endocytosis / physiology
  • Exons / genetics
  • Female
  • Fibroblasts / metabolism
  • Heparin / metabolism*
  • Humans
  • Hyperlipidemia, Familial Combined / genetics
  • Hyperlipidemia, Familial Combined / metabolism*
  • Interpersonal Relations
  • Lipoproteins, VLDL / analysis
  • Lipoproteins, VLDL / chemistry
  • Lipoproteins, VLDL / metabolism*
  • Male
  • Middle Aged
  • Pedigree
  • Phenotype
  • Point Mutation
  • Proteoglycans / metabolism*

Substances

  • Apolipoproteins E
  • Lipoproteins, VLDL
  • Proteoglycans
  • apolipoprotein E5
  • Heparin