Characterization of Cxorf5 (71-7A), a novel human cDNA mapping to Xp22 and encoding a protein containing coiled-coil alpha-helical domains

Genomics. 1998 Jul 15;51(2):243-50. doi: 10.1006/geno.1998.5348.

Abstract

The human X chromosome is known to contain several disease genes yet to be cloned. In the course of a project aimed at the construction of a transcription map of the Xp22 region, we fully characterized a novel cDNA, Cxorf5 (HGMW-approved symbol, alias 71-7A), previously mapped to this region but for which no sequence information was available. We isolated and sequenced the full-length transcript, which encodes a predicted protein of unknown function containing a large number of coiled-coild domains, typically presented in a variety of different molecules, from fibrous proteins to transcription factors. We showed that the Cxorf5 cDNA is ubiquitously expressed, undergoes alternative splicing, and escapes X inactivation. Furthermore, we precisely mapped two additional Cxorf5-related loci on the Y chromosome and on chromosome 5. By virtue of its mapping assignment to the Xp22 region, Cxorf5 represents a candidate gene for at least four human diseases, namely spondyloepiphiseal dysplasia late, oral-facial-digital syndrome type 1, craniofrontonasal syndrome, and a nonsyndromic sensorineural deafness.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alternative Splicing
  • Amino Acid Sequence
  • Chromosome Mapping*
  • Cloning, Molecular
  • DNA, Complementary / genetics*
  • Dosage Compensation, Genetic
  • Humans
  • Male
  • Molecular Sequence Data
  • Open Reading Frames / genetics
  • Organ Specificity
  • Physical Chromosome Mapping
  • Protein Structure, Secondary
  • Proteins / chemistry
  • Proteins / genetics*
  • RNA, Messenger / analysis
  • Sequence Analysis, DNA
  • X Chromosome / genetics*

Substances

  • DNA, Complementary
  • OFD1 protein, human
  • Proteins
  • RNA, Messenger

Associated data

  • GENBANK/Y15164
  • GENBANK/Y16355